Acute pulmonary embolism in a child with ANCA-negative Idiopathic Pulmonary Capillaritis.
Identifieur interne : 000B10 ( Main/Exploration ); précédent : 000B09; suivant : 000B11Acute pulmonary embolism in a child with ANCA-negative Idiopathic Pulmonary Capillaritis.
Auteurs : Ali A. Asseri [Oman] ; Yi Zeng ; Cori L. DainesSource :
- Saudi medical journal [ 0379-5284 ] ; 2019.
Descripteurs français
- KwdFr :
- Alvéoles pulmonaires, Anticorps anticytoplasme des polynucléaires neutrophiles, Douleur thoracique (étiologie), Embolie pulmonaire (diagnostic), Embolie pulmonaire (traitement médicamenteux), Embolie pulmonaire (étiologie), Enfant, Femelle, Humains, Hydroxychloroquine (administration et posologie), Hypoxie (étiologie), Hémorragie (étiologie), Héparine bas poids moléculaire (administration et posologie), Maladie aigüe, Maladies pulmonaires (étiologie), Poumon (), Prednisolone (administration et posologie), Résultat thérapeutique, Vaisseaux capillaires, Vascularite ().
- MESH :
- administration et posologie : Hydroxychloroquine, Héparine bas poids moléculaire, Prednisolone.
- diagnostic : Embolie pulmonaire.
- traitement médicamenteux : Embolie pulmonaire.
- étiologie : Douleur thoracique, Embolie pulmonaire, Hypoxie, Hémorragie, Maladies pulmonaires.
- Alvéoles pulmonaires, Anticorps anticytoplasme des polynucléaires neutrophiles, Enfant, Femelle, Humains, Maladie aigüe, Poumon, Résultat thérapeutique, Vaisseaux capillaires, Vascularite.
English descriptors
- KwdEn :
- Acute Disease, Antibodies, Antineutrophil Cytoplasmic, Capillaries, Chest Pain (etiology), Child, Female, Hemorrhage (etiology), Heparin, Low-Molecular-Weight (administration & dosage), Humans, Hydroxychloroquine (administration & dosage), Hypoxia (etiology), Lung (blood supply), Lung Diseases (etiology), Mercaptopurine (administration & dosage), Mercaptopurine (analogs & derivatives), Prednisolone (administration & dosage), Pulmonary Alveoli, Pulmonary Embolism (diagnosis), Pulmonary Embolism (drug therapy), Pulmonary Embolism (etiology), Treatment Outcome, Vasculitis (complications).
- MESH :
- chemical , administration & dosage : Heparin, Low-Molecular-Weight, Hydroxychloroquine, Mercaptopurine, Prednisolone.
- chemical , analogs & derivatives : Mercaptopurine.
- chemical : Antibodies, Antineutrophil Cytoplasmic.
- blood supply : Lung.
- complications : Vasculitis.
- diagnosis : Pulmonary Embolism.
- drug therapy : Pulmonary Embolism.
- etiology : Chest Pain, Hemorrhage, Hypoxia, Lung Diseases, Pulmonary Embolism.
- Acute Disease, Capillaries, Child, Female, Humans, Pulmonary Alveoli, Treatment Outcome.
Abstract
Diffuse alveolar hemorrhage is an uncommon and often fatal condition in children that is characterized by distinct histopathological etiologies. Herein, we discuss the case of an 11-year-old girl who presented with acute worsening of hypoxia and left-sided chest pain. The patient had lung biopsy-proven idiopathic pulmonary capillaritis and was being treated with prednisolone every alternate day, azathioprine, and hydroxychloroquine. A contrast-computed tomography (CT) scan of the chest showed an acute left lower-lobe pulmonary embolism. Negative results were obtained on a test for thrombophilia. In children, pulmonary embolism with anti-neutrophil cytoplasmic antibody-negative idiopathic pulmonary capillaritis is a rare clinical condition. The exact cause of thrombus formation in this case is unknown; however, obesity, immobility, and chronic systemic corticosteroid therapy probably played a role.
DOI: 10.15537/smj.2019.6.24210
PubMed: 31219497
Affiliations:
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Le document en format XML
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<country wicri:rule="url">Oman</country>
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<affiliation wicri:level="1"><nlm:affiliation>Department of Pediatrics, College of Medicine, King Khalid University, Abha, Kingdom of Saudi Arabia. E-mail. alsoheel11@gmail.com.</nlm:affiliation>
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<term>Antibodies, Antineutrophil Cytoplasmic</term>
<term>Capillaries</term>
<term>Chest Pain (etiology)</term>
<term>Child</term>
<term>Female</term>
<term>Hemorrhage (etiology)</term>
<term>Heparin, Low-Molecular-Weight (administration & dosage)</term>
<term>Humans</term>
<term>Hydroxychloroquine (administration & dosage)</term>
<term>Hypoxia (etiology)</term>
<term>Lung (blood supply)</term>
<term>Lung Diseases (etiology)</term>
<term>Mercaptopurine (administration & dosage)</term>
<term>Mercaptopurine (analogs & derivatives)</term>
<term>Prednisolone (administration & dosage)</term>
<term>Pulmonary Alveoli</term>
<term>Pulmonary Embolism (diagnosis)</term>
<term>Pulmonary Embolism (drug therapy)</term>
<term>Pulmonary Embolism (etiology)</term>
<term>Treatment Outcome</term>
<term>Vasculitis (complications)</term>
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<keywords scheme="KwdFr" xml:lang="fr"><term>Alvéoles pulmonaires</term>
<term>Anticorps anticytoplasme des polynucléaires neutrophiles</term>
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<term>Embolie pulmonaire (diagnostic)</term>
<term>Embolie pulmonaire (traitement médicamenteux)</term>
<term>Embolie pulmonaire (étiologie)</term>
<term>Enfant</term>
<term>Femelle</term>
<term>Humains</term>
<term>Hydroxychloroquine (administration et posologie)</term>
<term>Hypoxie (étiologie)</term>
<term>Hémorragie (étiologie)</term>
<term>Héparine bas poids moléculaire (administration et posologie)</term>
<term>Maladie aigüe</term>
<term>Maladies pulmonaires (étiologie)</term>
<term>Poumon ()</term>
<term>Prednisolone (administration et posologie)</term>
<term>Résultat thérapeutique</term>
<term>Vaisseaux capillaires</term>
<term>Vascularite ()</term>
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<term>Prednisolone</term>
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<keywords scheme="MESH" qualifier="etiology" xml:lang="en"><term>Chest Pain</term>
<term>Hemorrhage</term>
<term>Hypoxia</term>
<term>Lung Diseases</term>
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<term>Embolie pulmonaire</term>
<term>Hypoxie</term>
<term>Hémorragie</term>
<term>Maladies pulmonaires</term>
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<term>Capillaries</term>
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<term>Female</term>
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<term>Pulmonary Alveoli</term>
<term>Treatment Outcome</term>
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<term>Anticorps anticytoplasme des polynucléaires neutrophiles</term>
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<term>Humains</term>
<term>Maladie aigüe</term>
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<front><div type="abstract" xml:lang="en">Diffuse alveolar hemorrhage is an uncommon and often fatal condition in children that is characterized by distinct histopathological etiologies. Herein, we discuss the case of an 11-year-old girl who presented with acute worsening of hypoxia and left-sided chest pain. The patient had lung biopsy-proven idiopathic pulmonary capillaritis and was being treated with prednisolone every alternate day, azathioprine, and hydroxychloroquine. A contrast-computed tomography (CT) scan of the chest showed an acute left lower-lobe pulmonary embolism. Negative results were obtained on a test for thrombophilia. In children, pulmonary embolism with anti-neutrophil cytoplasmic antibody-negative idiopathic pulmonary capillaritis is a rare clinical condition. The exact cause of thrombus formation in this case is unknown; however, obesity, immobility, and chronic systemic corticosteroid therapy probably played a role.</div>
</front>
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<name sortKey="Zeng, Yi" sort="Zeng, Yi" uniqKey="Zeng Y" first="Yi" last="Zeng">Yi Zeng</name>
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